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CASE REPORT article

Front. Pediatr.
Sec. Pediatric Cardiology
Volume 12 - 2024 | doi: 10.3389/fped.2024.1437500
This article is part of the Research Topic Imaging, diagnosis and interventional treatment of congenital heart disease in children View all articles

Prenatal echocardiographic diagnosis of left pulmonary artery discontinuous with Taussing-Bing syndrome: case report and literature review

Provisionally accepted
Yun He Yun He 1Yufei Yang Yufei Yang 1Xiaoyu Song Xiaoyu Song 1Zhonglei Zhang Zhonglei Zhang 1Dingfang Yan Dingfang Yan 1Chao Xie Chao Xie 1Min Zeng Min Zeng 2Wenjun Zhang Wenjun Zhang 1*
  • 1 Department of Ultrasound Medicine, Taihe Hospital, Hubei University of Medicine, Shiyan, China
  • 2 Department of Cardiothoracic Surgery, Taihe Hospital, Hubei University of Medicine, Hubei, China

The final, formatted version of the article will be published soon.

    Background: Unilateral pulmonary artery discontinuity (UPAD) is a rare foetal abnormality, for which prenatal ultrasonographic diagnosis remains challenging. We report a case of left pulmonary artery discontinuity in association with Taussig-Bing syndrome, which has rarely been reported in literature so far.Case presentation: A pregnant woman with CHD at 23 weeks gestation was referred to our center. She denied any familial history of genetic disorders in both spouses and Noninvasive prenatal testing (NIPT) also showed low risk. An ultrasound examination revealed a complex cardiac malformation indicative of left pulmonary artery originating from the ductus arteriosus with Taussig-Bing syndrome. The family eventually chose to terminate a pregnancy and agreed to an autopsy, which confirmed that prenatal echocardiographic diagnosis was correct. In addition, we reviewed and analyzed 17 reported cases of prenatal echocardiographic diagnosis of UPAD.Conclusions: UPAD is characterized by discontinuity between the proximal and distal pulmonary arteries, along with a ductal origin of distal pulmonary artery. Discontinuous pulmonary artery originating from the ductus can be detected on prenatal sonography using ultrasound technology. The aim is to detect malformations earlier and carry out necessary intervention measures as soon as possible.

    Keywords: Fetus, Malformation, Pulmonary Artery, Echocardiography, Congenital heart

    Received: 23 May 2024; Accepted: 18 Nov 2024.

    Copyright: © 2024 He, Yang, Song, Zhang, Yan, Xie, Zeng and Zhang. This is an open-access article distributed under the terms of the Creative Commons Attribution License (CC BY). The use, distribution or reproduction in other forums is permitted, provided the original author(s) or licensor are credited and that the original publication in this journal is cited, in accordance with accepted academic practice. No use, distribution or reproduction is permitted which does not comply with these terms.

    * Correspondence: Wenjun Zhang, Department of Ultrasound Medicine, Taihe Hospital, Hubei University of Medicine, Shiyan, China

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